Alan Patrick Kenny1*, Jareen Meinzen-Derr2,3, Manish Patel N4, Kevin Bove1,5 and Henry Akinbi
1Department of Pediatrics, University of Cincinnati, USA
2Department of Neonatology, University of Cincinnati, USA
3Department of Otolaryngology, University of Cincinnati, USA
4Department of Radiology, University of Cincinnati, USA
5Department of Pathology and Laboratory Medicine, University of Cincinnati, USA
Pneumothoraces are a significant cause of neonatal respiratory distress. We report for the first time an infant with refractory recurrent unilateral left-sided pneumothoraces resulting from a pulmonary lymphangiectasia containing an infantile hemangioma. Known causes of recurrent pneumothoraces include both congenital and acquired lymphangiectasia. Infantile hemangiomas occur in viscera, especially liver, but presence in the lung is very rare. We postulate that lymphangiectasia in this infant was secondary to local lymphatic obstruction by the hemangioma. We recommend consideration of lymphangiectasia from an isolated mass such as congenital infantile hemangiomas in the differential as a newly identified cause of recurrent unilateral pneumothoraces. Established facts and novel insights: Established facts: Pneumothoraces are often caused by underlying neonatal lung pathology. Refractory recurrent unilateral pneumothoraxes are rare in the neonate. Novel insights: Infantile hemangioma can cause neonatal lung pathology. Congenital lymphangiectasia containing an infantile hemangioma for first time is reported to cause of refractory recurrent unilateral pneumothorax in the neonate.
Kenny AP, Meinzen-Derr J, Manish Patel N, Bove K, Henry Akinbi T. Focal Pulmonary Lymphangiectasia Containing an Infantile Hemangioma: An Unprecedented Cause of Refractory Recurrent Unilateral Pneumothoraces. Ann Clin Case Rep. 2019; 4: 1765.